Login / Signup

Expanding the phenotype in argininosuccinic aciduria: need for new therapies.

Julien BaruteauElisabeth JamesonAndrew A MorrisAnupam ChakrapaniSaikat SantraSuresh VijayHuriye KocadagClare E BeesleyStephanie GrunewaldElaine MurphyMaureen ClearyHelen MundyLara AbulhoulAlexander BroomfieldRobin LachmannYusof RahmanPeter H RobinsonLesley MacPhersonKatharine FosterW Kling ChongDeborah A RidoutKirsten McKay BounfordSimon N WaddingtonPhilippa B MillsPaul GissenJames E Davison
Published in: Journal of inherited metabolic disease (2017)
Our study further defines the natural history of argininosuccinic aciduria and genotype-phenotype correlations. The neurological phenotype does not correlate with the severity of hyperammonaemia and plasma argininosuccinic acid levels. The disturbance in nitric oxide synthesis may be a contributor to the neurological disease. Clinical trials providing nitric oxide to the brain merit consideration.
Keyphrases
  • nitric oxide
  • clinical trial
  • nitric oxide synthase
  • hydrogen peroxide
  • cerebral ischemia
  • white matter
  • resting state
  • multiple sclerosis
  • blood brain barrier
  • study protocol
  • phase ii
  • double blind