Deletion of transcription factor AP-2β from the developing murine trabecular meshwork region leads to progressive glaucomatous changes.
Aftab TaiyabMonica AkulaJapnit DhamPaula DeschampsHeather SheardownTrevor WilliamsTeresa BorrásJudith A West-MaysPublished in: Journal of neuroscience research (2021)
Glaucoma is one of the leading causes of irreversible blindness and can result from abnormalities in anterior segment structures required for aqueous humor outflow, including the trabecular meshwork (TM) and Schlemm's canal (SC). Transcription factors such as AP-2β play critical roles in anterior segment development. Here, we show that the Mgp-Cre knock-in (Mgp-Cre.KI) mouse can be used to target the embryonic periocular mesenchyme giving rise to the TM and SC. Fate mapping of male and female mice indicates that AP-2β loss causes a decrease in iridocorneal angle cells derived from Mgp-Cre.KI-expressing populations compared to controls. Moreover, histological analyses revealed peripheral iridocorneal adhesions in AP-2β mutants that were accompanied by a decrease in expression of TM and SC markers, as observed using immunohistochemistry. In addition, rebound tonometry showed significantly higher intraocular pressure (IOP) that was correlated with a progressive significant loss of retinal ganglion cells, reduced retinal thickness, and reduced retinal function, as measured using an electroretinogram, in AP-2β mutants compared with controls, reflecting pathology described in late-stage glaucoma patients. Importantly, elevated IOP in AP-2β mutants was significantly reduced by treatment with latanoprost, a prostaglandin analog that increases unconventional outflow. These findings demonstrate that AP-2β is critical for TM and SC development, and that these mutant mice can serve as a model for understanding and treating progressive human primary angle-closure glaucoma.
Keyphrases
- transcription factor
- optic nerve
- wild type
- induced apoptosis
- multiple sclerosis
- dna binding
- high resolution
- optical coherence tomography
- genome wide identification
- endothelial cells
- diabetic retinopathy
- cell cycle arrest
- ejection fraction
- end stage renal disease
- newly diagnosed
- signaling pathway
- metabolic syndrome
- mass spectrometry
- neoadjuvant chemotherapy
- adipose tissue
- endoplasmic reticulum stress
- prognostic factors
- oxidative stress
- long non coding rna
- skeletal muscle
- cataract surgery
- induced pluripotent stem cells
- patient reported outcomes
- smoking cessation
- patient reported