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Defective mitochondrial ATPase due to rare mtDNA m.8969G>A mutation-causing lactic acidosis, intellectual disability, and poor growth.

Pirjo IsohanniChristopher J CarrollChristopher B JacksonMax PohjanpeltoTuula LönnqvistAnu Suomalainen
Published in: Neurogenetics (2018)
Mutations in mitochondrial ATP synthase 6 (MT-ATP6) are a frequent cause of NARP (neurogenic muscle weakness, ataxia, and retinitis pigmentosa) or Leigh syndromes, especially a point mutation at nucleotide position 8993. M.8969G>A is a rare MT-ATP6 mutation, previously reported only in three individuals, causing multisystem disorders with mitochondrial myopathy, lactic acidosis, and sideroblastic anemia or IgA nephropathy. We present two siblings with the m.8969G>A mutation and a novel, substantially milder phenotype with lactic acidosis, poor growth, and intellectual disability. Our findings expand the phenotypic spectrum and show that mtDNA mutations should be taken account also with milder, stable phenotypes.
Keyphrases
  • intellectual disability
  • autism spectrum disorder
  • oxidative stress
  • mitochondrial dna
  • copy number
  • chronic kidney disease
  • spinal cord injury
  • skeletal muscle
  • gene expression
  • dna methylation