Genomic basis of syndromic short stature in an Algerian patient cohort.
Shahida MoosaFarida ChentliJanine AltmüllerNina BögershausenPeter NürnbergGökhan YigitYun LiBernd WollnikPublished in: American journal of medical genetics. Part A (2021)
Short stature is one of the most common reasons for a referral to the pediatric endocrinology clinic. Thousands of patients with short stature are assessed annually at the Department of Endocrine and Metabolic Diseases (DEMD) at Bab el Oued University Hospital in Algiers, Algeria. However, diagnostic rates in patients with syndromic short stature are not optimal due to the unavailability of next generation sequencing (NGS) technology. Here, we enrolled 10 Algerian patients with syndromic short stature in a pilot study to test the impact of genetic and genomic approaches in the DEMD. Using a combination of two different NGS modalities, namely exome sequencing and the Mendeliome (TruSight™ One sequencing panel) along with single gene testing, we were able to establish a confirmed molecular diagnosis in 7/10 patients (70%) and to identify strong likely disease-causing variants in a further two patients. Novel variants in NPR2 and VPS13B were identified. Using copy number variation analysis on the exome data, we also identified a de novo deletion of the short arm of chromosome X. These definitive diagnoses have made a substantial impact on patient treatment, management and genetic counseling. Genomic testing has the ability to transform clinical practice, and is an essential diagnostic tool in any tertiary pediatric clinic, particularly in resource limited settings.
Keyphrases
- copy number
- mitochondrial dna
- genome wide
- end stage renal disease
- dna methylation
- ejection fraction
- chronic kidney disease
- primary care
- newly diagnosed
- growth hormone
- intellectual disability
- case report
- peritoneal dialysis
- clinical practice
- prognostic factors
- patient reported outcomes
- gene expression
- autism spectrum disorder
- machine learning
- artificial intelligence
- hepatitis c virus
- squamous cell carcinoma
- radiation therapy
- young adults
- big data
- locally advanced
- hiv infected
- rectal cancer
- electronic health record
- data analysis
- replacement therapy
- antiretroviral therapy