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Whole exome sequencing uncovered highly penetrant recessive mutations for a spectrum of rare genetic pediatric diseases in Bangladesh.

Hosneara AkterMohammad Shahnoor HossainNushrat Jahan DityMd Atikur RahamanK M Furkan UddinNasna NassirGhausia BegumReem Abdel HameidMuhammad Sougatul IslamTahrima Arman TustyMohammad BasiruzzamanShaoli SarkarMazharul IslamSharmin JahanElaine T LimMarc Woodbury-SmithDimitri James StavropoulosDarren D O'RiellyBakhrom K BerdeivA H M Nurun NabiMohammed Nazmul AhsanStephen W SchererMohammed Uddin
Published in: NPJ genomic medicine (2021)
Collectively, rare genetic diseases affect a significant number of individuals worldwide. In this study, we have conducted whole-exome sequencing (WES) and identified underlying pathogenic or likely pathogenic variants in five children with rare genetic diseases. We present evidence for disease-causing autosomal recessive variants in a range of disease-associated genes such as DHH-associated 46,XY gonadal dysgenesis (GD) or 46,XY sex reversal 7, GNPTAB-associated mucolipidosis II alpha/beta (ML II), BBS1-associated Bardet-Biedl Syndrome (BBS), SURF1-associated Leigh Syndrome (LS) and AP4B1-associated spastic paraplegia-47 (SPG47) in unrelated affected members from Bangladesh. Our analysis pipeline detected three homozygous mutations, including a novel c. 863 G > C (p.Pro288Arg) variant in DHH, and two compound heterozygous variants, including two novel variants: c.2972dupT (p.Met991Ilefs*) in GNPTAB and c.229 G > C (p.Gly77Arg) in SURF1. All mutations were validated by Sanger sequencing. Collectively, this study adds to the genetic heterogeneity of rare genetic diseases and is the first report elucidating the genetic profile of (consanguineous and nonconsanguineous) rare genetic diseases in the Bangladesh population.
Keyphrases
  • copy number
  • genome wide
  • dna methylation
  • transcription factor
  • case report
  • autism spectrum disorder
  • early onset
  • tyrosine kinase
  • cerebral palsy
  • bioinformatics analysis