Different clinical phenotypes in familial severe congenital neutropenia cases with same mutation of the ELANE gene.
Hye Kyung ChoIn Sang JeonPublished in: Journal of Korean medical science (2014)
Severe congenital neutropenia (SCN) is a heterogeneous group of disorders with a defect in granulopoiesis causing marked neutropenia and severe bacterial infections. A 17-month-old girl (patient 1) was admitted due to cervical lymphadenitis caused by methicillin-resistant Staphylococcus aureus, with neutropenia. She had Pseudomonas aeruginosa sepsis and peritonitis with perforated appendicitis at 8-month of age. Her sister, a 37-month-old girl (patient 2), had recurrent stomatitis with profound neutropenia, and her mother, a 32-yr-old woman (patient 3), had had recurrent stomatitis until her early 20s with neutropenia. We found an ELANE gene mutation (c.597+1G > A) from them in direct DNA sequencing analysis. Patients 1 and 2 did not respond to granulocyte colony stimulating factor and patient 1 was treated with prolonged antibiotics and excision. We demonstrated inherited SCN cases showing different severity even with the same mutation of the ELANE gene in a family.
Keyphrases
- case report
- chemotherapy induced
- methicillin resistant staphylococcus aureus
- pseudomonas aeruginosa
- early onset
- newly diagnosed
- end stage renal disease
- staphylococcus aureus
- intensive care unit
- genome wide
- ejection fraction
- cystic fibrosis
- prognostic factors
- dna methylation
- gene expression
- chronic kidney disease
- peritoneal dialysis
- acinetobacter baumannii
- patient reported outcomes
- septic shock
- single molecule
- autism spectrum disorder
- intellectual disability
- multidrug resistant
- candida albicans
- patient reported
- soft tissue