Cell-binding IgM in CSF is distinctive of multiple sclerosis and targets the iron transporter SCARA5.
Ilaria CallegariJohanna OechteringMika SchneiderSylvain PerriotAmandine MathiasMargarete M VoortmanAlessandro CagolUlrike LannerMartin DieboldSebastian HoldermannVictor KreinerBurkhard BecherCristina GranzieraAndreas JunkerRenaud Du PasquierMichael KhalilJens KuhleLudwig KapposNicholas S R SandersonTobias DerfussPublished in: Brain : a journal of neurology (2024)
Intrathecal IgM production in multiple sclerosis is associated with a worse disease course. To investigate pathogenic relevance of autoreactive IgM in multiple sclerosis, CSF from two independent cohorts, including multiple sclerosis patients and controls, were screened for antibody binding to induced pluripotent stem cell-derived neurons and astrocytes, and a panel of CNS-related cell lines. IgM binding to a primitive neuro-ectodermal tumour cell line discriminated 10% of multiple sclerosis donors from controls. Transcriptomes of single IgM producing CSF B cells from patients with cell-binding IgM were sequenced and used to produce recombinant monoclonal antibodies for characterization and antigen identification. We produced five cell-binding recombinant IgM antibodies, of which one, cloned from an HLA-DR + plasma-like B cell, mediated antigen-dependent complement activation. Immunoprecipitation and mass spectrometry, and biochemical and transcriptome analysis of the target cells identified the iron transport scavenger protein SCARA5 as the antigen target of this antibody. Intrathecal injection of a SCARA5 antibody led to an increased T cell infiltration in an experimental autoimmune encephalomyelitis (EAE) model. CSF IgM might contribute to CNS inflammation in multiple sclerosis by binding to cell surface antigens like SCARA5 and activating complement, or by facilitating immune cell migration into the brain.
Keyphrases
- multiple sclerosis
- single cell
- white matter
- mass spectrometry
- cell migration
- cell therapy
- end stage renal disease
- rna seq
- binding protein
- oxidative stress
- signaling pathway
- chronic kidney disease
- gene expression
- stem cells
- blood brain barrier
- spinal cord injury
- cell free
- cerebrospinal fluid
- functional connectivity
- resting state
- amino acid