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Implementing a New Algorithm for Reinterpretation of Ambiguous Variants in Genetic Dilated Cardiomyopathy.

Alexandra Perez SerraRocío ToroEstefanía Martinez-BarriosAnna IglesiasAnna Fernandez-FalguerasMireia AlcaldeMónica CollMarta PuigmuléBernat Del OlmoFerran PicóLaura LopezElena ArbeloSergi CésarColoma Tiron de LlanoAlipio MangasJosep BrugadaGeorgia Sarquella BrugadaRamon BrugadaÒscar Campuzano
Published in: International journal of molecular sciences (2024)
Dilated cardiomyopathy is a heterogeneous entity that leads to heart failure and malignant arrhythmias. Nearly 50% of cases are inherited; therefore, genetic analysis is crucial to unravel the cause and for the early identification of carriers at risk. A large number of variants remain classified as ambiguous, impeding an actionable clinical translation. Our goal was to perform a comprehensive update of variants previously classified with an ambiguous role, applying a new algorithm of already available tools. In a cohort of 65 cases diagnosed with dilated cardiomyopathy, a total of 125 genetic variants were classified as ambiguous. Our reanalysis resulted in the reclassification of 12% of variants from an unknown to likely benign or likely pathogenic role, due to improved population frequencies. For all the remaining ambiguous variants, we used our algorithm; 60.9% showed a potential but not confirmed deleterious role, and 24.5% showed a potential benign role. Periodically updating the population frequencies is a cheap and fast action, making it possible to clarify the role of ambiguous variants. Here, we perform a comprehensive reanalysis to help to clarify the role of most of ambiguous variants. Our specific algorithms facilitate genetic interpretation in dilated cardiomyopathy.
Keyphrases
  • copy number
  • machine learning
  • heart failure
  • deep learning
  • genome wide
  • dna methylation
  • gene expression
  • working memory
  • atrial fibrillation
  • human health
  • congenital heart disease
  • acute heart failure