Curative allogeneic hematopoietic stem cell transplantation following reduced toxicity conditioning in adults with primary immunodeficiency.
Ambroise MarçaisNizar MahlaouiBénédicte NevenFanny LanternierÉmilie CatherinotHélène SalvatorMorgane CheminantMaxime JeljeliVahid AsnafiPeter Van EndertLouis-Jean CoudercOlivier LortholaryCapucine PicardDespina MoshousOlivier HermineAlain FischerFelipe SuarezPublished in: Bone marrow transplantation (2022)
Primary immunodeficiencies (PID) are heterogeneous inborn errors of the immune system. Allogeneic hematopoietic stem cell transplantation (allo-HSCT) is curative and safe at the pediatric age but remains underperformed in adults. We report our experience on 32 consecutive adult patients with various PID including 17 (53%) with a combined immune deficiency, six (19%) with a disease of immune dysregulation and nine (28%) with a chronic granulomatous disease (CGD) who underwent an allo-HSCT between 2011 and 2020. The median age at transplant was 27 years (17-41). All assessable patients engrafted. The majority of patients received a fludarabine-Busulfan (FB) based regimen (FB2-3 in 16, FB4 in 12). Overall survival (OS) was 80.4% (100% for CGD and 74% for other PID patients) at 9 months and beyond (median follow-up 51.6 months). Six patients died, all in the first-year post-transplant. Cumulative incidences of grade II-IV acute GVHD/chronic GVHD were 18%/22%. Stem cell source, GVHD prophylaxis and conditioning intensity had no impact on OS. All surviving patients had over 90% donor chimerism, immune reconstitution, no sign of active PID related complications and were clinically improved. Allo-HSCT is effective in young adults PID patients with an acceptable toxicity and should be discussed in case of life-threatening PID.
Keyphrases
- allogeneic hematopoietic stem cell transplantation
- end stage renal disease
- ejection fraction
- stem cells
- chronic kidney disease
- newly diagnosed
- prognostic factors
- young adults
- peritoneal dialysis
- acute lymphoblastic leukemia
- acute myeloid leukemia
- rheumatoid arthritis
- patient safety
- liver failure
- electronic health record
- free survival