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Complex movement disorder in a patient with heterozygous YY1 mutation (Gabriele-de Vries syndrome).

Maria Teresa Carminho-RodriguesDora SteelSergio B SousaGregor BrandtMichel GuipponiSacha LaurentSiv FokstuenAurea MorenAndré ZachariaElisabeth DirrenRenata OliveiraManju A KurianPierre R BurkhardJulien F Bally
Published in: American journal of medical genetics. Part A (2020)
YY1 mutations cause Gabriele-de Vries syndrome, a recently described condition involving cognitive impairment, facial dysmorphism and intrauterine growth restriction. Movement disorders were reported in 5/10 cases of the original series, but no detailed description was provided. Here we present a 21-year-old woman with a mild intellectual deficit, facial dysmorphism and a complex movement disorder including an action tremor, cerebellar ataxia, dystonia, and partial ocular apraxia as the presenting and most striking feature. Whole-exome sequencing revealed a novel heterozygous de novo mutation in YY1 [NM: 003403.4 (YY1): c.907 T > C; p.(Cys303Arg)], classified as pathogenic according to the ACMG guidelines.
Keyphrases
  • early onset
  • case report
  • cognitive impairment
  • deep brain stimulation
  • parkinson disease
  • photodynamic therapy
  • soft tissue
  • deep learning
  • single cell
  • clinical practice