Nail-Patella Syndrome: clinical and molecular data in 55 families raising the hypothesis of a genetic heterogeneity.
Jamal GhoumidFlorence PetitMuriel Holder-EspinasseAnne-Sophie JourdainJosé GuerraAnne Dieux-CoeslierMartin FigeacNicole PorchetSylvie Manouvrier-HanuFabienne EscandePublished in: European journal of human genetics : EJHG (2015)
Nail-Patella Syndrome (NPS) is a rare autosomal dominant condition comprising nail and skeletal anomalies. Skeletal features include dysplastic patellae and iliac horns, as well as scapula and elbow dysplasia. Nephropathy and glaucoma or intra-ocular hypertension can sometimes be present. NPS is due to variants affecting function in LMX1B, which encodes a LIM-homeodomain protein critical for limb, kidney and eye development. We describe the phenotype and the molecular data of 55 index patients and their 39 relatives presenting with typical NPS. We identified 38 different LMX1B anomalies, 19 of which were not reported before. In our series, 9% of families are not carriers of a LMX1B genomic alteration after extensive study of the coding and non-coding regions of the gene. One of the families showed no linkage to the LMX1B locus, raising the hypothesis of a genetic heterogeneity.
Keyphrases
- copy number
- genome wide
- end stage renal disease
- case report
- electronic health record
- single cell
- newly diagnosed
- blood pressure
- ejection fraction
- dna methylation
- chronic kidney disease
- big data
- transcription factor
- oxide nanoparticles
- prognostic factors
- patient reported outcomes
- data analysis
- amino acid
- binding protein
- genome wide association study