Prenatal profile of Pallister-Killian syndrome: Retrospective analysis of 114 pregnancies, literature review and approach to prenatal diagnosis.
Emanuela SalzanoS E RaibleM KaurA WilkensG SpertiR K TiltonL R BettiniA RoccaG CocchiA SelicorniL K ConlinD McEldrewR GuptaS ThakurKosuke IzumiI D KrantzPublished in: American journal of medical genetics. Part A (2018)
Pallister-Killian syndrome (PKS) is a tissue limited mosaic disorder, characterized by variable degrees of neurodevelopmental delay and intellectual disability, typical craniofacial findings, skin pigmentation anomalies and multiple congenital malformations. The wide phenotypic spectrum of PKS in conjunction with the mosaic distribution of the i(12p) makes PKS an underdiagnosed disorder. Recognition of prenatal findings that should raise a suspicion of PKS is complicated by the fragmentation of data currently available in the literature and challenges in diagnosing a mosaic diagnosis on prenatal testing. Ultrasound anomalies, especially congenital diaphragmatic hernia, congenital heart defects, and rhizomelic limb shortening, have been related to PKS, but they are singularly not specific and are not present in all affected fetuses. We have combined prenatal data from 86 previously published reports and from our cohort of 114 PKS probands (retrospectively reviewed). Summarizing this data we have defined a prenatal growth profile and identified markers of perinatal outcome which collectively provide guidelines for early recognition of the distinctive prenatal profile and consideration of a diagnosis of PKS as well as for management and genetic counseling.
Keyphrases
- men who have sex with men
- pregnant women
- intellectual disability
- electronic health record
- case report
- systematic review
- autism spectrum disorder
- big data
- gene expression
- randomized controlled trial
- gestational age
- genome wide
- machine learning
- data analysis
- soft tissue
- human immunodeficiency virus
- preterm birth
- hiv infected
- antiretroviral therapy