Login / Signup

Amyloid fibril polymorphism in the heart of an ATTR amyloidosis patient with polyneuropathy attributed to the V122Δ variant.

Yasmin AhmedBinh An NguyenShumaila AfrinVirender SinghBret M EversPreeti SinghRose PedrettiLanie WangParker BassettMaria Del Carmen Fernandez-RamirezMaja PekalaBarbara Kluve-BeckermanLorena Saelices
Published in: bioRxiv : the preprint server for biology (2024)
ATTR amyloidosis is a phenotypically heterogeneous disease characterized by the pathological deposition of transthyretin in the form of amyloid fibrils into various organs. ATTR amyloidosis may stem from mutations in variant (ATTRv) amyloidosis, or aging in wild-type (ATTRwt) amyloidosis. ATTRwt generally manifests as a cardiomyopathy phenotype, whereas ATTRv may present as polyneuropathy, cardiomyopathy, or mixed, in combination with many other symptoms deriving from secondary organ involvement. Over 130 different mutational variants of transthyretin have been identified, many of them being linked to specific disease symptoms. Yet, the role of these mutations in the differential disease manifestation remains elusive. Using cryo-electron microscopy, here we structurally characterized fibrils from the heart of an ATTRv patient carrying the V122Δ mutation, predominantly associated with polyneuropathy. Our results show that these fibrils are polymorphic, presenting as both single and double filaments. Our study alludes to a structural connection contributing to phenotypic variation in ATTR amyloidosis, as polymorphism in ATTR fibrils may manifest in patients with predominantly polyneuropathic phenotypes.
Keyphrases
  • wild type
  • multiple myeloma
  • heart failure
  • electron microscopy
  • case report
  • atrial fibrillation
  • high resolution
  • sleep quality
  • mass spectrometry
  • african american