Anti-MDA-5 antibody-positive clinically amyopathic dermatomyositis with rapidly progressive interstitial lung disease treated with therapeutic plasma exchange: A case series.
Tomohiro SaitoMasahide MizobuchiYusuke MiwaMotonori SugiyamaYuuki MimaAyana IidaNobuhiro KanazawaTomoki MorikawaJunichi HayashiKei FukudaYasuto ShikidaTaihei SuzukiHirokazu HondaPublished in: Journal of clinical apheresis (2020)
We present six cases of antimelanoma differentiation-associated gene 5 antibody (anti-MDA5-Ab)-positive clinically amyopathic dermatomyositis (CADM) with rapidly progressive interstitial lung disease (RP-ILD), which is known to have a poor prognosis. The outcomes of these cases are described after treatment with therapeutic plasma exchange (TPE). Clinical and therapeutic data for patients with CADM with RP-ILD were collected retrospectively from medical records. All six patients received early intensive care including high-dose corticosteroids, intravenous cyclophosphamide, and a calcineurin inhibitor, but lung disease and hypoxia became more severe. TPE was performed over a median of 9.5 sessions (range 3-14) per patient, and the median duration from admission to TPE was 23 days. Three patients received combined direct hemoperfusion using a polymyxin B-immobilized fiber column (PMX-DHP) therapy on successive days to manage acute respiratory failure. Four patients survived and two died due to respiratory failure. In the survival cases, ferritin decreased, and ferritin and KL-6 were lower at diagnosis. The patients who died had a higher alveolar-arterial oxygen difference and more severe lung lesions at the time of initiation of TPE. These findings indicate that a combination of conventional therapy and TPE may be useful for improvement of the prognosis of CADM with RP-ILD at the early stage of onset.
Keyphrases
- interstitial lung disease
- systemic sclerosis
- respiratory failure
- rheumatoid arthritis
- end stage renal disease
- idiopathic pulmonary fibrosis
- high dose
- poor prognosis
- ejection fraction
- newly diagnosed
- early stage
- extracorporeal membrane oxygenation
- healthcare
- low dose
- chronic kidney disease
- type diabetes
- peritoneal dialysis
- gene expression
- prognostic factors
- intensive care unit
- endothelial cells
- early onset
- genome wide
- acute respiratory distress syndrome
- ionic liquid
- signaling pathway
- free survival
- cell therapy
- lymph node
- cell proliferation
- copy number
- electronic health record
- rectal cancer
- metabolic syndrome
- multidrug resistant
- skeletal muscle