Progeria-based vascular model identifies networks associated with cardiovascular aging and disease.
Mzwanele NguboZhaoyi ChenDarin McDonaldRana KarimpourAmit ShresthaJulien Yockell-LelièvreAurélie LaurentOjong Tabi Ojong BesongEve C TsaiF Jeffrey DilworthMichael J HendzelWilliam Lloyd StanfordPublished in: Aging cell (2024)
Hutchinson-Gilford Progeria syndrome (HGPS) is a lethal premature aging disorder caused by a de novo heterozygous mutation that leads to the accumulation of a splicing isoform of Lamin A termed progerin. Progerin expression deregulates the organization of the nuclear lamina and the epigenetic landscape. Progerin has also been observed to accumulate at low levels during normal aging in cardiovascular cells of adults that do not carry genetic mutations linked with HGPS. Therefore, the molecular mechanisms that lead to vascular dysfunction in HGPS may also play a role in vascular aging-associated diseases, such as myocardial infarction and stroke. Here, we show that HGPS patient-derived vascular smooth muscle cells (VSMCs) recapitulate HGPS molecular hallmarks. Transcriptional profiling revealed cardiovascular disease remodeling and reactive oxidative stress response activation in HGPS VSMCs. Proteomic analyses identified abnormal acetylation programs in HGPS VSMC replication fork complexes, resulting in reduced H4K16 acetylation. Analysis of acetylation kinetics revealed both upregulation of K16 deacetylation and downregulation of K16 acetylation. This correlates with abnormal accumulation of error-prone nonhomologous end joining (NHEJ) repair proteins on newly replicated chromatin. The knockdown of the histone acetyltransferase MOF recapitulates preferential engagement of NHEJ repair activity in control VSMCs. Additionally, we find that primary donor-derived coronary artery vascular smooth muscle cells from aged individuals show similar defects to HGPS VSMCs, including loss of H4K16 acetylation. Altogether, we provide insight into the molecular mechanisms underlying vascular complications associated with HGPS patients and normative aging.
Keyphrases
- vascular smooth muscle cells
- cardiovascular disease
- smooth muscle
- coronary artery
- gene expression
- angiotensin ii
- genome wide
- single cell
- histone deacetylase
- dna methylation
- poor prognosis
- end stage renal disease
- chronic kidney disease
- dna repair
- ejection fraction
- transcription factor
- signaling pathway
- pulmonary artery
- pulmonary hypertension
- atrial fibrillation
- dna damage
- early onset
- left ventricular
- long non coding rna
- single molecule
- cell death
- patient reported outcomes
- blood brain barrier
- cell cycle arrest
- copy number
- endoplasmic reticulum stress
- brain injury
- binding protein
- aqueous solution
- genome wide analysis