Therapeutic Benefit of Galectin-1: Beyond Membrane Repair, a Multifaceted Approach to LGMD2B.
Mary L Vallecillo-ZúnigaPeter Daniel PoulsonJacob S LuddingtonChristian J ArnoldMatthew RathgeberBraden C KartchnerSpencer HayesHailie GillJonard C ValdozJonathan L SpallinoSeth GarfieldEthan L DodsonConnie M ArthurSean R StowellPam M Van RyPublished in: Cells (2021)
Two of the main pathologies characterizing dysferlinopathies are disrupted muscle membrane repair and chronic inflammation, which lead to symptoms of muscle weakness and wasting. Here, we used recombinant human Galectin-1 (rHsGal-1) as a therapeutic for LGMD2B mouse and human models. Various redox and multimerization states of Gal-1 show that rHsGal-1 is the most effective form in both increasing muscle repair and decreasing inflammation, due to its monomer-dimer equilibrium. Dose-response testing shows an effective 25-fold safety profile between 0.54 and 13.5 mg/kg rHsGal-1 in Bla/J mice. Mice treated weekly with rHsGal-1 showed downregulation of canonical NF-κB inflammation markers, decreased muscle fat deposition, upregulated anti-inflammatory cytokines, increased membrane repair, and increased functional movement compared to non-treated mice. Gal-1 treatment also resulted in a positive self-upregulation loop of increased endogenous Gal-1 expression independent of NF-κB activation. A similar reduction in disease pathologies in patient-derived human cells demonstrates the therapeutic potential of Gal-1 in LGMD2B patients.
Keyphrases
- oxidative stress
- signaling pathway
- skeletal muscle
- high fat diet induced
- poor prognosis
- newly diagnosed
- recombinant human
- end stage renal disease
- endothelial cells
- ejection fraction
- cell proliferation
- lps induced
- chronic kidney disease
- adipose tissue
- insulin resistance
- nuclear factor
- peritoneal dialysis
- molecular dynamics
- immune response
- long non coding rna
- physical activity
- molecular dynamics simulations
- inflammatory response
- patient reported outcomes
- combination therapy
- depressive symptoms
- toll like receptor
- simultaneous determination
- pluripotent stem cells